ATYPICAL FORM OF MELORHEOSTOSIS IMPROVED BY PAMIDRONATE

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Kaouther Saadallaoui Ben Hamida
Imen Ksontini
Hajer Rahali
Slim Mourali
Nadia Fejraoui
Habib Bouhaouala
M.Ridha Charfi
M.Hedi Dougui

Abstract

Background: Melorheostosis is a rare chronic bone disease of unknown etiology that often affects a single limb.
Aim: Report a new case of melorheostosis of the ribs improved by pamidronate infusions
Case: A 36 year old man without any medical history was admitted for a history of one month painful tumefaction on the 7th left rib. The diagnosis of melorheostosis of the rib and the tibia was made. Patient was treated by pamidronate infusions with useful and satisfactory outcome.

Keywords:

Melorheostosis, Rib, Pamidronate

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References

  1. Resnick D. Diagnosis of bone and joint disorders. 3rd ed Philadelphia: WB Saunders 1995.
  2. Reznik M, Guy W, Fried MD. Myelopathy associated with melorheostosis: a case report. Arch Phys Med Rehabil 2005; 86: 1495-7.
  3. Nasu K, Kuroki Y, Nawano S. Thoracic cage extend of melorheostosis depicted by multislice CT. Skeletal Radiology 2002;31:464-6.
  4. Chanda B, Russell W, Millner J. Surgical Resection of melorheostosis in the ribs. Ann Thorac Sureg 2007; 83: 1518 -9.
  5. Shivanand G, Srivastava DN. Melorheostosis with scleroderma. J clin Imag 2004; 28: 214 -215.
  6. Freyschmidt J. Melorheostosis: a review of 23 cases. Eur Radiol 2001; 11: 474 - 79.
  7. Brown RR, Steiner GC, Lehman W. Melorheostosis: case report with radiologic pathologic correlation. Skeletal radiol 2000; 29: 548 - 52.
  8. Ghai S. Sharma R, Ghai S. Mixed scerosing bone dysplasia a case report with literature review. J Clin Imagining 2003; 27: 203 -05.
  9. Biaou O, Avimadje M, Guira O, Adjagba A, Zannou M, Hauzeur JP. Melorheostosis with bilateral involvement in a black african patient. Joint Bone Spine 2004; 71: 70 - 72.
  10. Moulder E, Marsh C. Soft tissue knee contractue of the knee due to melorheostosis, treated by total knee arthroplasty. Knee 2006; 13: 395 - 6.
  11. Champion V, Gérard M, Reinert P, Soria I. Douleurs osseuses et papules blanchâtres chez un adolescent de 12ans. Arch Ped 2005 ; 12 : 1124 - 28
  12. Hoshi K, Amizuka N. Histopathological characterization of melorheostosis. Orthopedics. 2001; 24: 273 -7.
  13. Hellemans J, Debber P, Wright M. Germline LEMD3 mutations are rare in sporadic patients wuth isolated melorheostosis. Hum Mutat 2006; 27: 290
  14. Moreno Alvarez M J, Lazaro MA, Espada G, Barcelo HA. Linear scleroderma and melorheeostosis: case presentation and literature review. Clin Rheum 1996; 15: 389-93.
  15. Bied JC, Malsh C, Meunier P. Melorheostosis in adults. A propos of 2 cases of them treated with diphosphonate (EHDP). Rev Rhum Mal Osteoartic 1976; 43: 193 -9.
  16. Mora R, Guerreschi F, Fedeli A, Riva C. Un cas de mélorheostose traité par disphosphonate. Acta Orthop Belg 1986 ; 52 : 856- 61.
  17. Donath J, Poor G, Kiss C, Fornet B, Genant H. Atypical form of active melorheostosis and its treatment with bisphosphonate. Skeletal Radiol 2002; 31: 709- 13.
  18. Brantus JF, Meunier PJ. Effects of intravenous etidronate and oral corticosteroids in fibrodysplasia ossificans progressive. Clin Orthop 1998 ; 346 : 117 -20.
  19. Haibel H, Braun J, Maksymowych WP. Bisphosphonates- targeting in the treatment of spondyloarthritis. Clin EXPrheumatol 2002; 20:S162 - S166.
  20. Van offel JF. A J. Schuerwegh. Influence of cyclic intravenous pamidronate on proinflammatory monocytic cytokine profiles and bone density in rheumatoid arthritis treated with low dose prednisolone and methotrexate. Clin Exp Rheum 2001; 19:13-20
  21. Maksymowych WP, Jhangri GS, Fitzgerald AA. A six month randomized controlled double dlind dose response comparaison of intravenous pamidronate (60 mg versus 10 mg) in the treatment of nonsteroidal anti-inflammatory drug refractory ankylosing spondylitis. Arthritis Rheum 2002; 46:766-773.